Movement Disorders (revue)

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[18F]FDOPA PET and clinical features in parkinsonism due to manganism

Identifieur interne : 003A55 ( Main/Exploration ); précédent : 003A54; suivant : 003A56

[18F]FDOPA PET and clinical features in parkinsonism due to manganism

Auteurs : Brad A. Racette [États-Unis] ; Jo Ann Antenor [États-Unis] ; Lori Mcgee-Minnich [États-Unis] ; Stephen M. Moerlein [États-Unis] ; Tom O. Videen [États-Unis] ; Vikas Kotagal [États-Unis] ; Joel S. Perlmutter [États-Unis]

Source :

RBID : Pascal:05-0261841

Descripteurs français

English descriptors

Abstract

Manganese exposure reportedly causes a clinically and pathophysiologically distinct syndrome from idiopathic Parkinson's disease (PD). We describe the clinical features and results of positron emission tomography with 6-[18F]fluorodopa ([18F]FDOPA PET) of a patient with parkinsonism occurring in the setting of elevated blood manganese. The patient developed parkinsonism associated with elevated serum manganese from hepatic dysfunction. [18F]FDOPA PET demonstrated relatively symmetric and severely reduced [18F]FDOPA levels in the posterior putamen compared to controls. The globus pallidum interna had increased signal on Tl-weighted magnetic resonance imaging (MRI) images. We conclude that elevated manganese exposure may be associated with reduced striatal [18F]FDOPA uptake, and MRI may reveal selective abnormality within the internal segment of the pallidum. This case suggests that the clinical and pathophysiological features of manganese-associated parkinsonism may overlap with that of PD.


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Le document en format XML

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<term>Emission tomography</term>
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<term>Positon</term>
<term>Parkinsonisme</term>
<term>Exploration radioisotopique</term>
<term>Tomographie émission positon</term>
<term>Parkinson maladie</term>
<term>Manganèse</term>
</keywords>
<keywords scheme="Wicri" type="topic" xml:lang="fr">
<term>Manganèse</term>
</keywords>
</textClass>
</profileDesc>
</teiHeader>
<front>
<div type="abstract" xml:lang="en">Manganese exposure reportedly causes a clinically and pathophysiologically distinct syndrome from idiopathic Parkinson's disease (PD). We describe the clinical features and results of positron emission tomography with 6-[
<sup>18</sup>
F]fluorodopa ([
<sup>18</sup>
F]FDOPA PET) of a patient with parkinsonism occurring in the setting of elevated blood manganese. The patient developed parkinsonism associated with elevated serum manganese from hepatic dysfunction. [
<sup>18</sup>
F]FDOPA PET demonstrated relatively symmetric and severely reduced [
<sup>18</sup>
F]FDOPA levels in the posterior putamen compared to controls. The globus pallidum interna had increased signal on Tl-weighted magnetic resonance imaging (MRI) images. We conclude that elevated manganese exposure may be associated with reduced striatal [
<sup>18</sup>
F]FDOPA uptake, and MRI may reveal selective abnormality within the internal segment of the pallidum. This case suggests that the clinical and pathophysiological features of manganese-associated parkinsonism may overlap with that of PD.</div>
</front>
</TEI>
<affiliations>
<list>
<country>
<li>États-Unis</li>
</country>
<region>
<li>Missouri (État)</li>
</region>
<settlement>
<li>Saint-Louis (Missouri)</li>
</settlement>
<orgName>
<li>École de médecine (Université Washington de Saint-Louis)</li>
</orgName>
</list>
<tree>
<country name="États-Unis">
<region name="Missouri (État)">
<name sortKey="Racette, Brad A" sort="Racette, Brad A" uniqKey="Racette B" first="Brad A." last="Racette">Brad A. Racette</name>
</region>
<name sortKey="Antenor, Jo Ann" sort="Antenor, Jo Ann" uniqKey="Antenor J" first="Jo Ann" last="Antenor">Jo Ann Antenor</name>
<name sortKey="Kotagal, Vikas" sort="Kotagal, Vikas" uniqKey="Kotagal V" first="Vikas" last="Kotagal">Vikas Kotagal</name>
<name sortKey="Mcgee Minnich, Lori" sort="Mcgee Minnich, Lori" uniqKey="Mcgee Minnich L" first="Lori" last="Mcgee-Minnich">Lori Mcgee-Minnich</name>
<name sortKey="Mcgee Minnich, Lori" sort="Mcgee Minnich, Lori" uniqKey="Mcgee Minnich L" first="Lori" last="Mcgee-Minnich">Lori Mcgee-Minnich</name>
<name sortKey="Moerlein, Stephen M" sort="Moerlein, Stephen M" uniqKey="Moerlein S" first="Stephen M." last="Moerlein">Stephen M. Moerlein</name>
<name sortKey="Perlmutter, Joel S" sort="Perlmutter, Joel S" uniqKey="Perlmutter J" first="Joel S." last="Perlmutter">Joel S. Perlmutter</name>
<name sortKey="Perlmutter, Joel S" sort="Perlmutter, Joel S" uniqKey="Perlmutter J" first="Joel S." last="Perlmutter">Joel S. Perlmutter</name>
<name sortKey="Perlmutter, Joel S" sort="Perlmutter, Joel S" uniqKey="Perlmutter J" first="Joel S." last="Perlmutter">Joel S. Perlmutter</name>
<name sortKey="Perlmutter, Joel S" sort="Perlmutter, Joel S" uniqKey="Perlmutter J" first="Joel S." last="Perlmutter">Joel S. Perlmutter</name>
<name sortKey="Racette, Brad A" sort="Racette, Brad A" uniqKey="Racette B" first="Brad A." last="Racette">Brad A. Racette</name>
<name sortKey="Videen, Tom O" sort="Videen, Tom O" uniqKey="Videen T" first="Tom O." last="Videen">Tom O. Videen</name>
<name sortKey="Videen, Tom O" sort="Videen, Tom O" uniqKey="Videen T" first="Tom O." last="Videen">Tom O. Videen</name>
</country>
</tree>
</affiliations>
</record>

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